Neurointervention.  2021 Jul;16(2):185-189. 10.5469/neuroint.2021.00080.

Vertebral Artery Dissecting Aneurysm Causing Central Tapia’s Syndrome: A Case Report

• Shim YW
• Park JH
• Kim ST
• Baek JW
• Lee HG
• Ko JH
• Paeng SH
• Pyo SY
• Jin SC
• Jeong HW
• Jeong YG

• KMID: 2517746
• DOI: http://doi.org/10.5469/neuroint.2021.00080

Abstract

The central type of Tapia’s syndrome is an extremely rare presentation, characterized by unilateral paralysis of the vagal and hypoglossal nerves, contralateral hemiparesis, or hemihypesthesia. This report describes a case of a middle-aged patient who developed central Tapia’s syndrome due to a right vertebral artery dissecting aneurysm (VADA). The patient complained about swallowing difficulty and odynophagia. Right vocal cord paralysis, mild tongue deviation to the right side, left hypesthesia, and decreased temperature sensation with left hemiparesis were observed in neurologic exams. A right VADA and compression of the medulla oblongata due to the VADA were diagnosed on magnetic resonance imaging. Endovascular flow diversion of the right VADA was performed. After 1 year, all neurological symptoms and vocal cord paralysis were nearly resolved, but left hypesthesia remained with decreased nociception. We present and discuss how a VADA caused those symptoms and propose endovascular flow diversion as a treatment option.

Keyword

Vertebral artery dissection; Endovascular procedures; Medulla oblongata; High-resolution magnetic resonance imaging; Tapia’s syndrome

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