J Korean Orthop Assoc.  2013 Feb;48(1):49-53. 10.4055/jkoa.2013.48.1.49.

Angiolymphoid Hyperplasia with Eosinophilia of Distal Arm

• Yoon HK
• Kim SH
• Kim S
• Kang HJ

• KMID: 2106664
• DOI: http://doi.org/10.4055/jkoa.2013.48.1.49

Abstract

Angiolymphoid hyperplasia with eosinophilia (ALHE) and Kimura's disease were classified as same disease in the past. Since there are many different clinical and histopathological characteristics that warranted their distinction, they are classified as different disease now. Six cases of Kimura's disease in upper extremity have been reported in Korean literature but ALHE in upper extremity has not been reported yet. We experienced a case of surgically treated ALHE in the upper arm and report this case with review of literature.

Keyword

arm; angiolymphoid hyperplasia; eosinophilia

MeSH Terms

Angiolymphoid Hyperplasia with Eosinophilia
Arm
Eosinophilia
Upper Extremity

Figure

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  Figure 1 Photographs of the left elbow show soft tissue mass on medial aspect of distal arm.

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  Figure 2 Magnetic resonance images show 2 enlarged lymph nodes on medial aspect of left upper arm, high signal intensity on fat-suppressed T2-weighted image (A) and marginal enhancement on Gadolinium enhanced fat-suppressed T1-weighted image (B). Severe edema and inflammatory change in surrounding subcutaneous tissue are also observed.

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  Figure 3 (A) Operative finding and (B) gross finding of the specimen show a gray-pinkish, ill-defined mass which are blended into the surrounding subcutaneous tissue.

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  Figure 4 Microscopic finding shows vascular proliferation with plump vascular endothelial cell. Infiltration of the numerous lymphocytes and eosinopils around the vascular structure are observed (H&E stain, ×200).

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