J Korean Med Sci.  1993 Dec;8(6):476-481. 10.3346/jkms.1993.8.6.476.

Delayed-onset focal dystonia after diffuse cerebral hypoxia: two case reports

• Choi YC
• Lee MS
• Choi IS

• KMID: 1422021
• DOI: http://doi.org/10.3346/jkms.1993.8.6.476

Abstract

The delayed-onset focal dystonia is a rare sequela of cerebrovascular disease or diffuse cerebral hypoxic damage. The responsible lesion sites for the dystonia are variable and the pathogenesis is uncertain. We describe two children with delayed-onset focal dystonia as a complication of perinatal anoxia. The intervals between hypoxic insult and onset of dystonia were 6 years in one and 3 in the other cases. Our patients did not have a focal lesion; one had scattered white matter lesion and the other had a diffuse frontoparietal atrophy. Delayed-onset dystonia after perinatal anoxia can be also caused by non-focal lesion such as diffuse frontoparietal atrophy or cerebral white matter lesion with long interval delay.

Keyword

Delayed-onset dystonia; perinatal anoxia

MeSH Terms

Child
Dystonia/*etiology
Female
Humans
Hypoxia, Brain/*complications
Male
Time Factors