Various structural lesions as well as metabolic derangements cause choreoballism. Hyperglycemia can induce diverse neurologic dysfunctions. There are few case reports of dyskinesias associated with hyperglycemia or diabetic ketoacidosis. A 19-year-old girl with insulin dependent diabetes mellitus presented with bilateral choreoballism. She had diabetic ketoacidosis. Her dyskinesia improved with control of high blood glucose and ketoacidosis. Though she had bilateral basal ganglia calcification, the chance of its contribution to dyskinesia was very slim. We advise physicians to keep in mind that treatable hyperglycemia can cause dyskinesia.