J Korean Med Sci.  2008 Oct;23(5):895-897. 10.3346/jkms.2008.23.5.895.

Sacral Intraspinal Bronchogenic Cyst: A Case Report

• Ko KS
• Jeun SS
• Lee YS
• Park CK

• KMID: 1783079
• DOI: http://doi.org/10.3346/jkms.2008.23.5.895

Abstract

Intraspinal bronchogenic cysts are rare congenital cystic lesions. In all the reported cases, the cysts have been located in the cervical, upper thoracic or thoracolumbar segments. We report the case of an intraspinal bronchogenic cyst in the sacral location. We present the case of a 5-month-old female with a skin dimple in the midline over the sacral vertebra. Magnetic resonance image of the lumbar and sacral vertebra revealed a dermal sinus tract and an epidural cystic mass at the S2 level. The patient underwent the removal of the dermal sinus tract and the cyst. The cystic mass was shown to be connected to the subarachnoid space through a slender pedicle from the dura. The cyst was diagnosed to be a bronchogenic cyst based on the results of the histopathological examination. We conclude that intraspinal bronchogenic cysts may appear in the sacral location.

Keyword

Bronchogenic Cyst; Endodermal Cyst

MeSH Terms

Bronchogenic Cyst/diagnosis/pathology/*surgery
Epithelium/pathology/*surgery
Female
Humans
Infant
Lumbar Vertebrae/pathology
Magnetic Resonance Imaging/methods
Sacrum/pathology
Spinal Dysraphism/complications
Treatment Outcome

Figure

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  Fig. 1 Preoperative saggital T2-weighted (A) and T1-weighted (B) MRI showing a 1.3×0.5 cm oval cystic lesion at the S2 level. Also, MRI revealed a dermal sinus tract at the S2 level.

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  Fig. 2 Intraoperative photography demonstrating an epidural cystic mass.

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  Fig. 3 (A) The cyst was lined by one layer of epithelial cells and connective tissue was observed in the cystic wall (H&E, ×40). (B) The lining epithelial cells were the ciliated columnar respiratory epithelial cells. Smooth muscle is seen beneath the epithelial lining (×400).

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