Tuberc Respir Dis.  2006 Jun;60(6):678-683. 10.4046/trd.2006.60.6.678.

1 Case of Bronchial Leiomyoma with Intralobar Pulmonary Sequestration

• Jung BY
• Kim DH
• Park ES
• Han SH
• Kim YT
• Oh MH
• Lee SY
• Choi JS
• Na JO
• Seo KH
• Kim YH

• KMID: 1630807
• DOI: http://doi.org/10.4046/trd.2006.60.6.678

Abstract

Both bronchial leiomyoma and pulmonary sequestration are rare conditions, and to the best of our knowledge there are no reports of the two conditions coexisting. We report a female patient with bronchial leiomyoma with acquired pulmonary sequestration who presented with dyspnea, cough and purulent sputum. The patient had been treated for pneumonia at a local medical clinic. but was transferred to our clinic beacausr there was no clinical improvement. A 3-D computed tomography scan revealed a 1.5 cm sized mass near the distal portion of the left main bronchus and an anomalous artery arising from the aorta. The patient showed clinical improvement after a left lower lobectomy and a ligation of the anomalous artery.

Keyword

Bronchial leiomyoma; Pulmonary sequestration

MeSH Terms

Aorta
Arteries
Bronchi
Bronchopulmonary Sequestration*
Cough
Dyspnea
Female
Humans
Leiomyoma*
Ligation
Pneumonia
Sputum

Figure

• 

  Figure 1 Chest PA. (A) Initial film shows consolidation on left lower lobe. (B) Follow up film at 1 day on admission shows total collapse of left lung

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  Figure 2 Chest CT with CE. (A) Collapse of Left lower lobe due to 1.5 cm sized endobronchial mass (arrow) in distal portion of left main bronchus. (B) Multiple cystic lesion (arrow) at collapse lesion of left lower lobe. (C) Abnormal vessels (arrow) originated from descending aorta at reformed oblique coronal imaging.

• 

  Figure 3 Bronchoscopic finding. (A) An impacted mass-like lesion covered a whitish exudate around the distal main bronchus. (B) At 12 days after operation, there was no endobronchial lesion

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  Figure 4 Microscopic finding of pulmonary sequestration. Multicystic spaces lined by cuboidal to columnar epithelium with intervening fibrosis and inflammation (H&E, ×100).

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  Figure 5 Microscopic findings of leiomyoma. (A) The tumor is formed by interlacing bundles of spindle cells, which has elongated nuclei and eosinophilic fibrillary cytoplasm (H&E, ×200). (B) Immunohistochemically, the tumor shows a diffuse positive reaction for smooth muscle actin (×200).

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